Tongue shaped oropharyngeal teratoma with cleft palate in a neonate: A case report

Authors

  • Samiul Hasan Dhaka Shishu (Children) Hospital, Dhaka, Bangladesh https://orcid.org/0000-0001-5470-2241
  • Nadia Afroz National Institute of Mental Health, Dhaka, Bangladesh
  • Jiaul Reza Dhaka Shishu (Children) Hospital, Dhaka, Bangladesh

DOI:

https://doi.org/10.52783/jns.v10.929

Keywords:

Oropharyngeal teratoma, Cleft palate, Neonatal tumor, Epignathus

Abstract

Background: Atypical presentation of an atypical abnormality makes the diagnosis challenging. Oropharyngeal teratoma (epignathus) is a rare, potentially life-threatening neonatal tumor. Its atypical presentation may cause a delay in diagnosis and increase morbidity and mortality.

Case presentation: A newborn girl with oropharyngeal teratoma and cleft palate presented with feeding difficulty. The airway was patent. The tumor was tongue-shaped, smooth-walled, displacing the native tongue, and prevented the fusion of two palatine halves resulting in cleft palate. On the 4th day of life, complete excision was done transorally. Histopathology revealed a mature teratoma. There was no sign of recurrence at three months of follow-up.

Conclusion: Presentation of the oropharyngeal teratoma varies according to its site, size, and extension. Timely diagnosis is essential to avoid life-threatening respiratory obstruction. Complete excision of the mass is usually associated with a good prognosis.

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References

Bahgat M, Bahgat Y, Bahgat A. Oropharyngeal teratoma, a rare cause of airway obstruction in neonates. BMJ Case Rep. 2012; 2012:bcr2012006580.

Kirishima M, Yamada S, Shinya M, Onishi S, Goto Y, Kitazono I, et al. An autopsy case of epignathus (immature teratoma of the soft palate) with intracranial extension but without brain invasion: case report and literature review. Diagn Pathol. 2018; 13:99.

Chauhan DS, Guruprasad Y, Inderchand S. Congenital nasopharyngeal teratoma with a cleft palate: case report and a 7 year follow up. J Maxillofac Oral Surg. 2011; 10:253-6.

Kishi Y, Soh S, Tanaka S, Nitta A, Matsushima A. A case of congenital teratoma with cleft palate in a neonate. Arch Clin Med Case Rep. 2020; 4:746-53.

Aubin A, Pondaven S, Bakhos D, Lardy H, Robier A, Lescanne E. Oropharyngeal teratomas in newborns: Management and outcome. Eur Ann Otorhinolaryngol Head Neck Dis. 2014; 131:271-5.

Posod A, Griesmaier E, Brunner A, Pototschnig C, Trawöger R, Kiechl-Kohlendorfer U. An unusual cause of inspiratory stridor in the newborn: congenital pharyngeal teratoma--a case report. BMC Pediatr. 2016; 16:1.

Jie H, Yanan W, Hanguang Z, Weiliu Q, Yue H. Nasopharyngeal teratoma associated with cleft palate in newborn: report of 2 cases. Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 2010; 109:211-6.

Morof D, Levine D, Grable I, Barnewolt C, Estroff J, Fishman S, et al. Oropharyngeal teratoma: prenatal diagnosis and assessment using sonography, MRI, and CT with management by ex utero intrapartum treatment procedure. Am J Roentgenol. 2004; 183:493-6.

Manchali MM, Sharabu C, Latha M, Kumar L. A rare case of oropharyngeal teratoma diagnosed antenatally with MRI. J Clin Imaging Sci. 2014; 4:15.

Kontopoulos EV, Gualtieri M, Quintero RA. Successful in utero treatment of an oral teratoma via operative fetoscopy: case report and review of the literature. Am J Obstet Gynecol. 2012; 207:e12-5.

Published

2021-02-23

How to Cite

1.
Hasan S, Afroz N, Reza J. Tongue shaped oropharyngeal teratoma with cleft palate in a neonate: A case report. J Neonatal Surg [Internet]. 2021Feb.23 [cited 2025Jun.19];10:13. Available from: https://jneonatalsurg.com/index.php/jns/article/view/929